DM1_DMPK

Gene
DMPK
Disease
DM1
Inheritance
AD
Classification
Definitive
Total Score
18
Publications Reviewed
6
Publication Span
25.28 years
Last Updated
07/21/2025
Curator(s)
Laurel Hiatt

Genetic evidence

Total: 12

Collective EvidenceAllelePMID:32851192 PMID:396438392Interruptions impact phenotype/onset; several studies have shown correlation between allele length and onset/disease severity
Singular EvidenceProbandsPMID:20635151650 patients
StatisticsCase-Control DataPMID:78470634Case-control study was carried out on 25 patients with myotonic dystrophy (MyD) and 25 healthy subjects (p < 0.0001)
3 rows

Experimental evidence

Total: 6

RescueRescue in non-human model organismPMID:399327942MBNL overexpression rescues cardiac phenotypes in a myotonic dystrophy type 1 heart mouse model
RescueRescue in cell culturePMID:160271111Knock-down of endogenous hnRNP H expression by siRNAs in cells expressing an EGFP gene fused to CUG repeats leads to release of nuclear sequestrated transcripts and restoration of EGFP expression
ModelsNon-human model organismPMID:316499612Alkaline phosphatase-positive pericytes from skeletal muscle of a transgenic mouse model
Functional AlterationPatient cellsPMID:316499611Alkaline phosphatase-positive pericytes from skeletal muscle of DM1 patients
4 rows

Note: Maximum score caps apply at evidence type, category, and supercategory levels, so section totals may be lower than the raw sum of row scores.